Case report: first diagnosis of VEXAS Syndrome in Costa Rica

 

محفوظ في:
التفاصيل البيبلوغرافية
المؤلفون: Masís-Mejía, Rodrigo, Brenes-Piedra, Luis Miguel, Jiménez-Solera, María Paz, Santamaría-Quesada, Carlos, Gallegos-Mesén, Alejandra, Sánchez-Benavides, Marvin
التنسيق: artículo original
الحالة:Versión publicada
تاريخ النشر:2025
الوصف:Introduction: VEXAS syndrome (Vacuoles, E1 enzyme, X-linked, Autoinflammatory, Somatic) is an autoinflammatory condition caused by somatic mutations in the UBA1 gene on the X chromosome. Materials: We present the case of a 65-year-old male with relapsing polychondritis admitted with severe systemic inflammation, fever, deep vein thrombosis, and myelodysplasia. Infectious and rheumatologic causes were ruled out. Results: Genetic sequencing confirmed a UBA1 mutation. Conclusion: Steroid treatment led to rapid clinical improvement and decreased inflammatory parameters.
البلد:Portal de Revistas UCR
المؤسسة:Universidad de Costa Rica
Repositorio:Portal de Revistas UCR
اللغة:Español
OAI Identifier:oai:portal.ucr.ac.cr:article/61773
الوصول للمادة أونلاين:https://revistas.ucr.ac.cr/index.php/medica/article/view/61773
كلمة مفتاحية:Síndrome VEXAS, gen UBA1, autoinflamatorio, síndrome mielodisplásico, reporte de caso
VEXAS syndrome, UBA1 gene, autoinflammatory disease, myelodysplastic syndrome, case report